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Abstract Details

Voltage-Gated Potassium Channel Antibody-Mediated Encephalitis in Siblings
Autoimmune Neurology
P2 - Poster Session 2 (5:30 PM-6:30 PM)
15-027
Demonstrate the heterogeneous nature of autoimmune encephalitidies
Encephalopathy associated with neuronal voltage-gated potassium channel (VGKC) antibodies is a rare disorder associated with a group of heterogeneous syndromes that include symptoms such as memory loss, seizures, neuromyotonia, and psychiatric manifestations.
Describe successive cases of VGKC encephalopathy in siblings
A 7 year old white male presents with 4 day history of nausea, vomiting, headache and altered mental status.  Initially thought to be infectious meningoencephalitis, an extensive infectious workup was negative. MRI showed diffuse enhancement of the meninges. Lumbar puncture showed lymphocytic pleocytosis and mildly elevated protein. His clinical state worsened to a near catatonia. He was started on empiric high-dose steroids with minimal improvement. He was soon after started on IVIG therapy. A serum encephalopathy panel returned positive for VGKC antibodies, with negative LGI1 and CSPR2 antibodies. His remaining symptoms consist of decreased attention and emotional lability.

 

Two years later, his 7-year-old younger brother presented with a two-day history of acute onset paranoid behaviors with tactile, auditory and visual hallucinations.  Initial studies including MRI, EEG, LP, infectious work-up were unrevealing.  He was empirically started on IVIG and high-dose steroids due to concern for autoimmune encephalitis, as his brother had.  His serum encephalopathy panel returned positive for VGKC, negative LGI1 and CSPR2. Patient showed improvement with steroids and IVIG, although has had several relapses and was recently started on rituximab.

VGKC encephalopathy can manifest in a variety of ways as seen in these brothers; one who presented with a picture of meningoencephalitis and catatonia, and the other with more acute onset paranoid psychosis and mania. This raises the possibility of an underlying genetic predisposition, little research is taking place in the genetics of VGKC encephalopathy. No genetic markers are known at this time, family studies may be warranted to deduce candidate genes.
Authors/Disclosures
Kiel Woodward, MD (UNMC)
PRESENTER
Dr. Woodward has nothing to disclose.
Alexandria Valdrighi, MD (University of California, San Francisco) Dr. Valdrighi has nothing to disclose.
Geetanjali S. Rathore, MD, FAAN (Childrens NEBRASKA) Dr. Rathore has nothing to disclose.
Mary C. Rickard, MD (Children's Hospital Medical Center) Dr. Rickard has nothing to disclose.