好色先生

好色先生

Explore the latest content from across our publications

Log In

Forgot Password?
Create New Account

Loading... please wait

Abstract Details

Studying Clinical and Genetic Characteristics of Emery-Dreifuss Muscular Dystrophy
Neuromuscular and Clinical Neurophysiology (EMG)
P11 - Poster Session 11 (8:00 AM-9:00 AM)
1-008

To investigate the clinical and genetic features of patients with Emery Dreifuss muscular dystrophy (EDMD) in Turkey.

EDMD is an inherited myopathy characterized by early contractures, slow progressive muscle weakness and cardiac involvement. The most common types are X-linked EDMD-1 and OD linked EDMD-2.  

Herein, we evaluated clinical and genetic findings of 23 patients from 11 unrelated families diagnosed with EDMD at the Department of Neurology, Istanbul Faculty of Medicine between 1989 and 2019.

Nineteen patients from 8 unrelated families (71%) diagnosed with EDMD-1, two patients from 2 families (18%) with EDMD-2, two patients from 1 family (9%) with rare EDMD-3. In EDMD-1 group, the mean onset age of disease was 5.5 ± 2.4 years, the most common initial sign was toe walking due to Achilles contracture. Scapuloperoneal muscle weakness distribution was the most common phenotypical feature. Cardiac involvement was observed in 90% of the patients during follow-up period and pace maker was implanted in 55% of them. Furthermore, 40% of female carriers had severe cardiac conduction defects.

Although the number of laminopathy patients were limited, the age of onset in  EDMD-2 patients was found earlier. The distribution of muscle weakness was scapulo-humero-peroenal. In addition, gluteus maximus and adductor muscles were affected earlier and one patient showed early and serious respiratory involvement. Two patients diagnosed with EDMD-3 had scapulo-humero-peroneal muscle weakness with significant atrophy of pectoral, vastus lateralis and medialis muscles.

Seven mutations were found in EMD, four of them (c.416_417delTT; c.248_252delTACTC; c.19delC; Q44X [c.130C> T]) were novel. Two heterozygous (c.1357C>T; c.127G>A  ) and one homozygous novel mutation (c.71C> G) were found in LAMIN A/C

Hereby, this cohort is the largest study from Turkey, indicates genotypic and phenotypic heterogeneity of EDMD and expands genetic mutation spectrum. 

Authors/Disclosures
Gulshan Yunisova, MD (Koç University Hospital, Muscle Disease Center)
PRESENTER
Dr. Yunisova has nothing to disclose.
Piraye Serdaroglu, MD (Istanbul University School of Medicine) No disclosure on file
Feza Deymeer, MD (Memorial Sisli Hospital) No disclosure on file
No disclosure on file
Fatma Yesim Parman, MD (Istanbul Üniversitesi Tip Fakültesi) Dr. Parman has nothing to disclose.
Hacer Durmus, MD (Department of Neurology, Istanbul Faculty of Medicine) Dr. Durmus has nothing to disclose.