Magnetic resonance imaging revealed bilateral frontal and left parietal haemorrhagic infarct and contrast venography revealed superior sagittal sinus thrombosis. Patient received low molecular weight heparin with two antiepileptics. His thrombophilia testing was positive for lupus anticoagulant and serum homocysteine was elevated. He was prescribed intravenous cyanocobalamin 1000 mcg along with thiamine 100 mg and pyridoxine 100 mg in combination daily for 7 days and then weekly. On day 3 of admission, his GCS improved to E4V5M6 with no seizure recurrence.  On re-examination at day 3, patient had a rare combination of AEC with MI and OA. By day 10 of admission, all these oculomotor abnormalities subsided.

Non-motor signs of eye have been previously reported in other pathologies involving the frontal and parietal cortex. However, this combination of both OA and AEC with MI in a patient of Cerebral venous sinus thrombosis (CVST) is the first case report to the best of our knowledge.