好色先生

好色先生

Explore the latest content from across our publications

Log In

Forgot Password?
Create New Account

Loading... please wait

Abstract Details

May Steroids Wake You Up! A Rare Case of Diencephalic Syndrome of Neuromyelitis Optica Spectrum Disorder
Autoimmune Neurology
P2 - Poster Session 2 (2:45 PM-3:45 PM)
021

We discuss a rare, atypical presentation of Neuromyelitis Optica spectrum disorder(NMOSD),  diagnostic and treatment strategies.

Diencephalic syndrome of NMOSD is a rare variant accounting for 3.4 %1 of NMOSD presentations. Usual clinical features include narcolepsy, hypothermia, SIADH, anorexia, daytime somnolence and obesity.

Not applicable

A 19-year-old African American female presented acutely with headache, nausea, emesis, blurring of vision followed by hallucinations. Her sodium was noted to be 119. MRI Brain and pituitary obtained during this time demonstrated infiltrative signal abnormality in hypothalamus, thalamus and mamillary bodies. Diagnosis of SIADH was made and hyponatremia was corrected as per guidelines. Patient returned to her baseline.

She presented 2 weeks later with headache and acute memory loss which progressed to hypothermia, bradycardia and somnolence.   She was drowsy but answering to questions with vigorous stimulation.  MRI Brain showed worsening infiltrative signal abnormality extending into midbrain, thalamus, basal ganglia with contrast enhancement. She was empirically started on broad spectrum antibiotics, thiamine and Methylprednisolone 125mg Q6H. Initial labs were remarkable for low Vitamin B1 and elevated CSF protein.  MR Spectroscopy showed decreased NAA and elevated choline peak.  MRI orbits showed features concerning for bilateral optic neuritis. MethylPrednisolone dose was increased to 1g daily and she completed a 4 day course along with 3 day course of IVIG. Clinically, patient's mentation improved; hypothermia and bradycardia resolved. Repeat MRI Brain showed improving signal alteration. AQP 4 antibody returned positive. Patient was discharged home after 5 day course of Plasmapheresis. 

Repeat MRI Brain obtained after 4 months of hospital discharge showed significantly  improved signal abnormalities. Clinically patient has been stable without any relapse.

We discuss a rare presentation of NMOSD presenting with SIADH, hypothermia, bradycardia, and somnolence. Differentials include CNS neoplasms, nutritional and metabolic disorders, and other infiltrative disorders. Treatment is empiric with steroids, IVIG, plasmapheresis and immune modulation.

Authors/Disclosures
Gowri Anil Peethambar, MBBS (Prisma Health , University of South Carolina, SOM)
PRESENTER
Dr. Anil Peethambar has nothing to disclose.
Juber D. Shaikh, MD, DM (neurology) (Prisma Health Richland Hospital Neurology) Dr. Shaikh has nothing to disclose.
Rashmi Singh, Sr., MD (Prisma Health - Midlands Prisma Health Richland Hospital) Dr. Singh has nothing to disclose.
Yedatore S. Venkatesh, MD, FAAN (University of SC School of Medicine) Dr. Venkatesh has nothing to disclose.
Renu Pokharna, MD, FAAN Dr. Pokharna has nothing to disclose.
Souvik Sen, MD, MS (USC Neurology) Dr. Sen has nothing to disclose.